Authors: Masaharu Oishi Shugo Ueda Sachiko Honjo Hiroyuki Koshiyama Yoshiaki Yuba Arimichi Takabayashi
Publish Date: 2012/05/23
Volume: 42, Issue: 10, Pages: 973-977
Abstract
Cavernous hemangioma of the adrenal gland is a rare tumor which does not usually have endocrinological function We report to our knowledge the third documented case of a functioning adrenal hemangioma Interestingly this tumor indicated glucocorticoid hypersecretion whereas the two previous cases showed mineralocorticoid hypersecretion The tumor was 5 cm in diameter with typical computed tomography and magnetic resonance imaging findings Subclinical Cushing’s syndrome was diagnosed preoperatively as there was insufficient suppression of cortisol by lowdose dexamethasone a low adrenocorticotropic hormone ACTH concentration and diminished ACTH and cortisol circadian rhythms without the typical clinical manifestation and symptoms of hypercortisolism Intraoperative hypotension occurred immediately after tumor removal and following postoperative adrenal insufficiency which support that the tumor was hyperfunctioning The postoperative adrenal insufficiency had recovered completely by 12 months after the operation
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